Laryngotracheal stenosis requiring emergency tracheostomy as the first manifestation of childhood-relapsing polychondritis
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6
Tipo de produção
article
Data de publicação
2013
Editora
PUBLISAUDE-EDICOES MEDICAS LDA
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Citação
ACTA REUMATOLOGICA PORTUGUESA, v.38, n.3, p.208-211, 2013
Resumo
Relapsing polychondritis is a rare childhood disorder of unknown etiology, characterized by inflammatory; recurrent and destructive cartilage lesions. The chondritis could be widespread and involves generally laryngeal and auricular hyaline cartilages. We described a 9 years and 4 months old girl, who presented recurrent acute laryngotracheitis and laryngotracheal stenosis, which were the first manifestations of relapsing polychondritis, and was submitted to emergency tracheostomy. She also had ear condritis and arthritis, being treated with prednisolone and methotrexate. In conclusion, we reported a rare case of relapsing polychondritis that presented a life-threatening laryngo-tracheo-bronchial disorder requiring tracheostomy. We suggest that the diagnosis of relapsing polychondritis should be considered for patients who present recurrent acute laryngotracheitis with other types of condritis, as well as musculoskeletal manifestations.
Palavras-chave
Polychondritis, Childhood, Laryngeal stenois, Tracheostomy
Referências
- Belot A, 2010, J PEDIATR-US, V156, P484, DOI 10.1016/j.jpeds.2009.09.045
- CLARK LJ, 1992, J LARYNGOL OTOL, V106, P841, DOI 10.1017/S002221510012105X
- DOLAN DL, 1966, AM J MED, V41, P285, DOI 10.1016/0002-9343(66)90023-4
- Edrees A, 2011, RHEUMATOL INT, V31, P707, DOI 10.1007/s00296-010-1775-9
- FOIDART JM, 1978, NEW ENGL J MED, V299, P1203, DOI 10.1056/NEJM197811302992202
- Fonseca AR, 2012, RHEUMATOL I IN PRESS
- ISAAK BL, 1986, OPHTHALMOLOGY, V93, P681
- Kent Peter D., 2004, Current Opinion in Rheumatology, V16, P56, DOI 10.1097/00002281-200401000-00011
- Kim CM, 2003, PEDIATR PULM, V35, P314, DOI 10.1002/ppul.10247
- Lahmer T, 2010, AUTOIMMUN REV, V9, P540, DOI 10.1016/j.autrev.2010.02.016
- Letko E, 2002, SEMIN ARTHRITIS RHEU, V31, P384, DOI 10.1053/sarh.2002.32586
- Lipnick RN, 1999, J RHEUMATOL, V18, P98
- Luckey P, 2001, AM J ROENTGENOL, V176, P61
- MCADAM LP, 1976, MEDICINE, V55, P193, DOI 10.1097/00005792-197605000-00001
- MICHET CJ, 1986, ANN INTERN MED, V104, P74
- Ozen S, 2010, ANN RHEUM DIS, V69, P798, DOI 10.1136/ard.2009.116657
- PEARSON CM, 1960, NEW ENGL J MED, V263, P51, DOI 10.1056/NEJM196007142630201
- Trepel RJ, 1989, J ADOLESC HLTH CARE, P557